Absence of memory B cells in patients with common variable immunodeficiency.

نویسندگان

  • Kazunaga Agematsu
  • Takeshi Futatani
  • Sho Hokibara
  • Norimoto Kobayashi
  • Masaya Takamoto
  • Satoshi Tsukada
  • Harumi Suzuki
  • Shigeo Koyasu
  • Toshio Miyawaki
  • Kazuo Sugane
  • Atsushi Komiyama
  • Hans D Ochs
چکیده

The molecular basis of common variable immunodeficiency (CVID) is unknown. To assess humoral immunity in CVID, we selected 24 patients with early or late onset of disease. X-linked agammaglobulinemia (XLA), X-linked hyper-IgM syndrome (XHIM), and non-XHIM were excluded based on clinical phenotype, assessment of the immune response, presence of Bruton's tyrosine kinase (Btk) in monocytes or platelets, and normal expression of CD40 ligand by activated T cells. The number of circulating B cells was within the normal range or reduced. IgD(-) CD27(+) memory B cells were markedly reduced or absent in all 24 patients and IgD(+) CD27(+) B cells were diminished in 8 patients. Circulating B cells from all 6 patients examined, including CVID patients with IgD(+) CD27(+) cells, failed to undergo somatic hypermutation in immunoglobulin-variable (V)-region genes, similar to cord blood B cells. B cells from CVID patients produced IgM and IgG, but not IgA upon the engagement of Ig receptor and CD40 in the presence of IL-2 and IL-10. B cells from all but 5 patients secreted IgE when stimulated by CD40 crosslinking in the presence of IL-4. The observation of defective memory B cells with abnormal cell marker expression and function demonstrates that naive CVID B cells including those expressing IgD(+) CD27(+), in analogy to cord blood and hyper-IgM syndrome B cells, may be responsible for their failure to differentiate into plasma cells and to produce high-affinity antibodies of different isotypes.

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عنوان ژورنال:
  • Clinical immunology

دوره 103 1  شماره 

صفحات  -

تاریخ انتشار 2002